Odontogenic keratocyst (OKC) is aggressive compared to other odontogenic cysts, but its malignant transformation is extremely rare. Odontogenic carcinoma may arise from an odontogenic cyst such as OKC. Here in, we introduce a case of odontogenic carcinoma assumed to have arisen from a preexisting OKC. Abnormal clinical and radiologic features seen in a previous or existing cyst may be warning signs of malignant transformation.

• 임기현(연세대학교 치과대학병원 구강악안면외과) | Kihyun Im (Department of Oral and Maxillofacial Surgery, Dental Hospital, Yonsei University)
• 한다울(연세대학교 치과대학병원 구강병리과) | Dawool Han (Department of Oral Pathology, Dental Hospital, Yonsei University)
• 김정헌(연세대학교 치과대학병원 구강악안면외과) | Junghun Kim (Department of Oral and Maxillofacial Surgery, Dental Hospital, Yonsei University)
• 남웅(연세대학교 치과대학병원 구강악안면외과) | Woong Nam (Department of Oral and Maxillofacial Surgery, Dental Hospital, Yonsei University) Correspondence